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RECRUITING
NCT05371613
PHASE2/PHASE3

A Study to Determine the Efficacy and Safety of Tividenofusp Alfa (DNL310) vs Idursulfase in Pediatric and Young Adult Participants With Neuronopathic (nMPS II) or Non-Neuronopathic Mucopolysaccharidosis Type II (nnMPS II)

Sponsor: Denali Therapeutics Inc.

View on ClinicalTrials.gov

Summary

This is a Phase 2/3, multiregional, two-arm, double-blind, randomized, active (standard-of-care)-controlled study of the efficacy and safety of tividenofusp alfa (DNL310), an investigational central nervous system (CNS)-penetrant enzyme-replacement therapy (ERT) for mucopolysaccharidosis type II (MPS II). Participants may also qualify to enter an open-label treatment phase with DNL310 or idursulfase based on pre-specified criteria.

Official title: A Phase 2/3, Multicenter, Double-Blind, Randomized Study to Determine the Efficacy and Safety of Tividenofusp Alfa (DNL310) vs Idursulfase in Pediatric and Young Adult Participants With Neuronopathic or Non-Neuronopathic Mucopolysaccharidosis Type II

Key Details

Gender

All

Age Range

2 Years - 25 Years

Study Type

INTERVENTIONAL

Enrollment

63

Start Date

2022-07-21

Completion Date

2027-12

Last Updated

2025-08-05

Healthy Volunteers

No

Interventions

DRUG

tividenofusp alfa

Intravenous repeating dose

DRUG

idursulfase

Intravenous repeating dose

Locations (32)

UCSF Benioff Children's Hospital Oakland

Oakland, California, United States

Ann and Robert H Lurie Children's Hospital of Chicago

Chicago, Illinois, United States

Hackensack University Medical Center

Hackensack, New Jersey, United States

UNC Children's Research Institute

Chapel Hill, North Carolina, United States

Cincinnati Children's Hospital Medical Center

Cincinnati, Ohio, United States

Children's Hospital of Philadelphia

Philadelphia, Pennsylvania, United States

The University of Texas Medical School at Houston

Houston, Texas, United States

University of Utah, PPDS

Salt Lake City, Utah, United States

Sanatorio Mater Dei

Buenos Aires, Argentina

Women's and Children's Hospital

North Adelaide, Australia

UZ Antwerpen

Antwerp, Antwerpen, Belgium

Universitair Ziekenhuis Brussel

Jette, Brussels Capital, Belgium

Hospital de Clínicas de Porto Alegre (HCPA) - PPDS

Porto Alegre, Brazil

Instituto Fernandes Figueira

Rio de Janeiro, Brazil

University of Alberta - Faculty of Medicine & Dentistry

Edmonton, Alberta, Canada

Hospital for Sick Children

Toronto, Ontario, Canada

McGill University Health Center

Montreal, Quebec, Canada

Vseobecna Fakultni Nemocnice V Praze

Prague, Czechia

Hôpital Jeanne de Flandre

Lille, France

SphinCS

Höchheim, Hochheim, Germany

Medizinische Universität Lausitz - Carl Thiem

Cottbus, Germany

Azienda Sanitaria Universitaria Friuli Centrale - PO Universitario Santa Maria della Misericordia

Udine, Italy

Erasmus Medical Center - Sophia Children's Hospital

Rotterdam, Rotterdam, Netherlands

Hospital Universitario Vall d'Hebron

Barcelona, Barcelona, Spain

Hospital Infantil Universitario Niño Jesus

Madrid, Madrid, Spain

Drottning Silvias Barn Och Ungdomssjukhus

Gothenburg, Sweden

Cukurova University Medical Faculty Balcali Hospital

Adana, Turkey (Türkiye)

Gazi Universitesi Tip Fakultesi

Çankaya, Turkey (Türkiye)

Great Ormond Street Hospital for Children

London, London, United Kingdom

Birmingham Women's and Children's NHS Foundation Trust

Birmingham, United Kingdom

Royal Free Hospital

London, United Kingdom

Salford Royal Hospital

Salford, United Kingdom